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Sibling Relationship Quality and Psychosocial Outcomes among Adult Siblings of Individuals
with Autism Spectrum Disorder and Individuals with Intellectual Disability without Autism
University
Author Note: This work was not supported by any funding agencies, and the authors have no
conflicts of interest to report.
CITATION:
Tomeny, T. S., Ellis, B. M., Rankin, J. A., & Barry, T. D. (2017). Sibling relationship quality
and psychosocial outcomes among adult siblings of individuals with autism spectrum
Abstract
disabilities remains limited, and outcomes for TD siblings appear to vary widely. For the current
study, 82 adult TD siblings of individuals with autism spectrum disorder (ASD) or intellectual
disability (ID) completed questionnaires about themselves and their affected sibling. Results of
this study suggest that the attitudes possessed by adult TD siblings are important to consider
when understanding adult TD sibling outcomes. Specifically, data indicate that higher levels of
positive sibling relationship attitudes are related to TD siblings providing more aid/support to
their sibling with a disability, along with having higher levels of general life satisfaction, and
negatively related to levels of stress and depressive symptoms among TD siblings. Consistent
with previous child research, siblings of individuals with ASD reported fewer positive sibling
relationship attitudes compared to siblings of individuals with ID. Finally, group membership
related to aid provided, depressive symptoms, and stress of TD siblings indirectly through sibling
relationship attitudes. Overall, results indicate that sibling relationship attitudes may be
particularly important to consider when conceptualizing sibling relationships when one sibling
Attitudes
SIBLING RELATIONSHIP QUALITY 3
This study helps to fill gaps in the literature on adult typically-developing (TD) siblings of
outcomes: sibling relationship attitudes. The results of this paper indicate that TD siblings of
individuals with ASD may possess less positive attitudes about their sibling relationships
attitudes were associated with TD sibling outcomes (e.g., stress, depressive symptoms, life
satisfaction) and amount of support that TD siblings provide their affected sibling. Due to rising
rates of diagnoses and a healthcare system already in crisis with regard to care for adults with
developmental disabilities, siblings likely will be increasingly charged with assuming care after
parents are no longer able. Thus, clinicians must be ready to assist TD siblings in this role, and
improving attitudes and views about the sibling relationship may be one approach to consider.
SIBLING RELATIONSHIP QUALITY 4
Individuals with Autism Spectrum Disorder and Individuals with Intellectual Disability
without Autism
1. Introduction
According to the United States Census Bureau, data collected in 2010 indicated that 0.4%
of the population (i.e., about 1.2 million adults) had intellectual disability (ID), whereas the
1.5% of the population (Baio, 2014). Moreover, a significant portion of individuals with ASD
also have co-occurring ID (e.g., Levy et al., 2010). These numbers alone are noteworthy, but it
also is important to consider that each individual’s disability is likely to impact their family
members. Having a family member with a developmental disability (DD) places unique demands
on those within the family unit and may have implications for the outcomes and functioning of
all those involved (McHale & Gamble, 1989; Roper, Allred, Mandleco, Freeborn, & Dyches,
2014; Tozer & Atkin, 2015). It would seem that those closely connected to individuals with a
DD may require support services themselves, substantially raising the number of individuals
2. Sibling Relationships
Generally, siblings seem to have strong and persistent influence over one another’s
development, life choices, outcomes, and functioning compared to individuals fulfilling other
roles in a person’s life. As Cicirelli (1995) observed, sibling relationships span a greater expanse
relationships generally the longest lasting relationships in a person’s life. The longevity of this
particular familial relationship and the far-reaching nature of disability underscore the
SIBLING RELATIONSHIP QUALITY 5
of individuals with a DD. Further, healthy functioning and positive outcomes in TD siblings is
particularly relevant to the disabled sibling because, as adults, many TD siblings may assume the
primary caregiver role once parents can no longer do so (Coyle, Kramer, & Mutchler, 2014).
Adult siblings of individuals with a DD often play important, supportive roles to their
siblings with DD (Atkin & Tozer, 2014). Most adult siblings in this population indicate that they
desire to be involved in the care of their sibling (Tozer & Atkin, 2015), with many expecting to
provide assistance in the future if they are not already doing so (Burke, Fish, & Lawton, 2015).
Relatedly, TD siblings have expressed difficulty in balancing the demands of caring for their
own family, caring for their aging parents, and being consistently involved with their siblings
with ASD (Tozer & Atkin, 2015). Duignan and Connell’s (2015) study suggests that caring for
an individual with ASD can alter the home environment in ways that result in negative effects on
siblings’ social relationships. Many TD siblings expect to assume greater caregiving roles when
their parents get older (Coyle et al., 2014), especially if they have a closer relationship with their
sibling (Burke, Taylor, Urbano, & Hodapp, 2012; Heller & Kramer, 2009). Thus, consideration
of adult sibling relationships is of particular interest when assessing the outcomes and
(Hastings & Petalas, 2014), particularly in adults (Ferraioli & Harris, 2009). Adult siblings of
individuals with a DD have unique sibling relationships as compared to similar but younger
sibling dyads (Orsmond, Kuo, & Seltzer, 2009), adult siblings of individuals with other types of
SIBLING RELATIONSHIP QUALITY 6
diagnoses (e.g., psychiatric, chronic health conditions), and TD sibling dyads (e.g., Hodapp &
Urbano, 2007). Whereas the closeness of sibling relationships appears to fluctuate in typical
sibling dyads (Orsmond et al.), closeness of siblings when one has a DD appears more stable
over time (Orsmond & Seltzer, 2007). Thus any social and emotional difficulties related to a lack
of closeness in the early sibling relationship may continue into adulthood (Orsmond & Seltzer,
2007). Furthermore, TD siblings of individuals with a DD who report positive, rewarding, close
sibling relationships also tend to have good health and perceive benefits of being a sibling to a
brother/sister with disabilities (Hodapp & Urbano, 2007; Hodapp, Urbano, & Burke, 2010).
psychosocial adjustment outcomes in adulthood (Dunn, Slomkowski, Beardsall, & Rende, 1994;
Waldinger, Vaillant, & Orav, 2007). Considering the longevity and impact of this relationship, it
DDs when compared to siblings within typical dyads appears inconsistent, with some siblings
exhibiting positive outcomes (Macks & Reeve, 2007), some negative outcomes (Gold, 1993;
Verté, Roeyers, & Buysse, 2003), and some no differences (Di Biasi et al., 2015; Tomeny, Barry,
& Bader, 2012). As suggested by Seltzer, Greenberg, Orsmond, and Lounds (2005), these
inconsistencies in TD siblings’ outcomes may be dependent upon their siblings’ type of DD.
Rossiter and Sharpe’s (2001) meta-analysis suggests that the type of disability and its severity
are what influence the effects of the disability on the TD siblings. Caroli and Sagone (2013)
found that youth TD siblings (ages 13 to 18 years) of individuals with ASD had more negative
social attitudes toward their disabled siblings and more negative emotions than did TD siblings
SIBLING RELATIONSHIP QUALITY 7
of individuals with Down syndrome (DS) or ID. Alternatively, TD siblings of children with DS
have reported higher levels of relationship quality and social support within the sibling
relationship (Pollard, Barry, Freedman, & Kotchick, 2013) and viewed their sibling more
positively (Mandleco & Webb, 2015) than TD siblings of children with ASD.
The limited research on adults suggests that TD siblings of individuals with ASD
experience more depressive symptoms and poorer health compared to TD siblings of adults with
DS (Hodapp & Urbano, 2007). Further, TD siblings of adults with ID report more positive affect,
closeness, and compassion in the sibling relationship compared to siblings of adults with ASD
(Orsmond & Seltzer, 2000). Though few, these studies support the need for further investigation
6. Current Study
Given the substantial number of individuals in the U.S. with a DD, the longevity of
sibling relationships (Cicirelli, 1995), and the unique demands placed upon the families of
individuals with a DD (McHale & Gamble, 1989; Roper et al., 2014; Tozer & Atkin, 2015), it is
important to examine the functioning and outcomes of TD siblings of individuals with a DD.
Research displaying the differential effects of ID and ASD on TD siblings’ functioning warrants
further examination of group differences. Because most studies to date have focused on
differences in youth siblings of individuals with various mental disabilities, the current study
aims to build upon current literature by examining similar factors among adult siblings of
First, it was expected that sibling relationship quality would predict amount of
aid/support provided by TD siblings, TD sibling life satisfaction, and depressive, anxiety and
stress symptoms in TD siblings over and above demographic correlates (Hypothesis 1). Second,
SIBLING RELATIONSHIP QUALITY 8
we hypothesized that TD siblings of those with ASD would report significantly lower levels of
positive sibling relationship attitudes compared to siblings of individuals with ID without ASD
(Hypothesis 2). We then conducted exploratory post hoc analyses based on results from
Hypotheses 1 and 2 that examined indirect effects between group inclusion (ASD vs. ID) and TD
7. Method
7.1. Participants
ASD provided data about themselves and their sibling with a disability. The ASD group was
siblings with ASD ages 18 to 52 (M = 26.49, SD = 8.55; 20% were female). The ID without ASD
SD = 13.07; 86% were female) and siblings with ID ages 19 to 55 (M = 35.24, SD = 12.71; 49%
were female). Those within the ID group were of mixed etiology and had disorders such as
Down Syndrome, Cerebral Palsy, Fragile X, and intellectual disability not otherwise specified.
Across both groups, 4.67 years was the average absolute value of sibling age differences and
63% of respondents were older than their sibling with a disability. The racial distribution of the
other. Thirty-two percent of TD siblings reported making over $100,000 annually, 42% reported
being married, and 38% described themselves as never married or living alone.
Few respondents (i.e., four) described themselves as the primary caregiver of their
sibling. However, across both groups, 43% reported providing direct care [defined as “assistance
SIBLING RELATIONSHIP QUALITY 9
with activities of daily living (e.g., grooming, feeding, household chores)”] at least once per
month (15% reported daily direct care), 51% reported providing transportation at least once per
month (15% reported daily transportation assistance), 28% reported providing financial
assistance at least once per month (13% reported providing daily financial assistance), and 40%
reported running errands for their sibling at least once per month (16% reported performing daily
errands).
7.2. Measures
data (e.g., age, gender, ethnicity, marital status, income, level of education) about themselves and
their sibling with a DD, along with information about their siblings’ diagnosis (e.g., specific
diagnosis, age of diagnosis, who made the diagnosis) via a demographic and diagnostic
measured via this questionnaire: a Total score was calculated by summing responses to five
questions on a 5-point Likert scale (0 = none to 4 = daily or almost daily) about amount of direct
care, transportation, financial assistance, errands completed, and “other” care provided.
7.2.2. Depression Anxiety and Stress Scale. The Depression, Anxiety, and Stress Scale
(DASS; Lovibond & Lovibond, 1995) is a 21-item self-report measure of distress. Using a 0
(Did not apply to me) to 3 (Applied to me very much, or most of the time) scale, respondents rate
how much each item applied to them during the previous week. The DASS provides a Total
scale and Depression, Anxiety, and Stress subscales. Scale scores are calculated by multiplying
the sum of scores by two to allow for comparisons to the 42-item version of the DASS per
Lovibond and Lovibond (1995). Example items from the DASS include “I found it difficult to
relax” and “I was unable to become enthusiastic about anything.” The DASS has shown
SIBLING RELATIONSHIP QUALITY 10
appropriate convergent validity and internal consistency in previous research (Lovibond &
Lovibond, 1995), and coefficient alphas for the current sample ranged from .80 to .91 for the
subscales.
7.2.3. Lifespan Sibling Relationship Scale. The Lifespan Sibling Relationship Scale
(LSRS; Riggio, 2000) is a self-report adult measure of sibling relationship quality and attitudes.
The LSRS aims to provide an overall assessment of relationship quality by measuring affective,
report on current and retrospective attitudes, and they were asked to think about their sibling with
a disability when completing this measure. The LSRS is composed of 48 items on a 5-point
Likert scale from 1 (Strongly disagree) to 5 (Strongly agree) and higher scores indicate more
positive attitudes about the sibling relationship. The LSRS produces six subscale scores that
childhood and adulthood. Example items include: “My sibling is a good friend” and “My sibling
and I often helped each other as children.” The LSRS also produces a Total score, which was of
interest for the current study. Previous psychometric research suggests that the LSRS shows
appropriate validity and reliability, and this validity appears to remain stable across the lifespan
(Riggio, 2000). The LSRS Total scale produced a coefficient alpha of .96 for the current sample,
7.2.4. Satisfaction with Life Scale. The Satisfaction with Life Scale (SWLS) is a brief 5-
item measure of overall life satisfaction (Diener, Emmons, Larsen, & Griffin, 1985).
Respondents are asked to rate the extent to which they agree with each statement using a 7-point
Likert scale from 1 (Strongly Disagree) to 7 (Strongly agree). Example items include: “I am
satisfied with my life” and “The conditions of my life are excellent.” The total scale produced a
SIBLING RELATIONSHIP QUALITY 11
coefficient alpha of .89, suggesting good internal reliability for the current sample, consistent
7.3. Procedure
Data were collected following approval from the University Institutional Review Board
and provision of electronic consent by each participant. TD siblings were recruited via
were sent a link to a secure survey website on which study questionnaires were stored and
completed. Seventy-three percent of those TD siblings who accessed the survey completed the
study. After consent, TD siblings completed a Demographic and Diagnostic form, the DASS, the
LSRS, and the SLS. TD siblings were instructed to consider their sibling with a DD when
8. Results
Less than 0.01% of data was missing at the item-level; the mean of the items on
respective scales was imputed to replace missing data according to Harrell (2001). Group
differences among variables of interest are listed in Table 1. Intercorrelations of the variables of
Possible control variables for Hypothesis 1 and the post hoc analyses were determined
using zero-order correlations between the possible control variables and the criterion variables
for the total sample (Table 3). TD sibling depression was negatively correlated with TD sibling
income and marital status (dichotomized: 0 = living alone, 1 = living with a significant other).
TD sibling anxiety and stress were also negatively associated with TD sibling income, and TD
SIBLING RELATIONSHIP QUALITY 12
sibling stress was positively associated with birth order of siblings with DD. Aid/support was
positively correlated with age discrepancy (absolute value), distance between siblings, and birth
order of siblings with DD and was negatively correlated with TD sibling race (dichotomized: 0 =
nonwhite, 1 = white). As such, TD sibling income, TD sibling marital status, birth order of
siblings with DD, age discrepancy, distance between siblings, and TD sibling race were included
as covariates when their respective criterion variables were examined for Hypothesis 1 and post
hoc analyses.
Because the ASD and ID groups were not matched on demographic variables,
independent samples t-tests were conducted to examine group differences in possible confounds
for Hypothesis 2 (Table 4). Results revealed that the two groups differed in gender of sibling
with a disability (coded 1 = male, 2 = female), t(80) = 2.79, p = .007, TD sibling age, t(80) =
2.54, p = .01, TD sibling birth order, t(80) = 3.28, p = .002, and number of people in their
household during childhood, t(79) = 2.74, p = .009. In order to maximize statistical power via
conservative use of degrees of freedom (Cepeda, Boston, Farrar, & Strom, 2003) when
examining group differences, propensity scores were calculated according to procedures outlined
by Rosenbaum and Rubin (1983). The aforementioned variables were entered into a binary
logistic regression as predictors of group membership (ASD vs. ID), and the probability scores
from these logistic regressions were saved and served as a single covariate when examining
group differences. Although the groups also differed on age of siblings with a DD, this variable
was not included as a covariate due to its strong association with TD sibling age (r = .88, p <
.001).
8.2. Hypothesis 1
SIBLING RELATIONSHIP QUALITY 13
Hypothesis 1 (that sibling relationship attitudes would predict amount of aid provided by
sibling stress across the whole sample) was tested via a series of multiple regression analyses
(Table 5). Statistically determined covariates (Table 3) were entered in Step 1 of their respective
analyses. Sibling relationship attitudes were entered in Step 2. Positive sibling relationship
attitudes were positively associated with aid provided by TD siblings, ΔF(5, 76) = 7.65, p = .01,
ΔR2 = .07, and TD sibling life satisfaction, ΔF(1, 79) = 6.31, p = .01, ΔR2 = .07. Alternatively,
positive sibling relationship attitudes were negatively associated with TD sibling depression,
ΔF(3, 77) = 9.33, p = .003, ΔR2 = .09, and stress, ΔF(3, 78) = 4.78, p = .03, ΔR2 = .05. Sibling
relationship attitudes did not predict TD sibling anxiety, ΔF(2, 78) = 1.69, p = .20, ΔR2 = .02.
8.3. Hypothesis 2
Hypothesis 2 (that TD siblings of individuals with ASD would have significantly lower
levels of positive sibling relationship attitudes compared to TD siblings of individuals with ID)
was examined via an analysis of covariance. On average, TD siblings of individuals with ASD
of siblings with a disability, TD sibling age, TD sibling birth order, and childhood family size
constant. Analyses were conducted twice (with separate covariates and with the propensity
scores as a single covariate); each analysis yielded significant group differences: F(1,75) = 7.07,
p = .01, when using separate covariates, F(1,78) = 7.55, p = .01, when using the propensity
score.
Given the group differences in sibling relationship attitudes and the relations between
pathway exists between group membership (ASD vs. ID) and (1) aid provided by, (2) life
satisfaction, (3) depression, and (4) stress in TD siblings through sibling relationship attitudes.
Although a total effect between group membership and outcomes in TD siblings was not found, a
total effect between the predictor and the criterion variable is not a precursor for determining
meaningful indirect effects (Hayes, 2013). Despite the lack of evidence of a direct relation, it
could be that TD sibling group membership relates to outcomes in TD siblings in an indirect way
Indirect effects (i.e., the product of the effect for the path between group membership and
sibling relationship attitudes and the effect for the path between sibling relationship attitudes and
each criterion variable; i.e., path a X path b; Hayes, 2013) were examined using bootstrapping
methods to estimate bias-corrected asymmetric confidence intervals (CIs) of the indirect effects
with 5000 resamples with replacement. A CI not inclusive of zero indicates a significant indirect
effect (Preacher & Hayes, 2008). These bootstrap analyses were conducted using Hayes’s (2013)
PROCESS macro tool for SPSS. Aforementioned propensity scores were entered as a control
variable to account for group differences in demographic variables during each analysis.
Additional control variables were entered based on their bivariate relations with each respective
criterion variable (Table 4). Specifically, siblings with a DD birth order, geographic distance
age difference between siblings (absolute value) were entered as control variables when
predicting amount of aid provided. Age difference between siblings (absolute value) and age of
siblings with a DD served as control variables when predicting TD sibling life satisfaction.
SIBLING RELATIONSHIP QUALITY 15
When predicting TD sibling depression, TD sibling marital status (dichotomized: 1 = living with
a significant other, 0 = living alone) and TD sibling income were entered as control variables.
When predicting TD sibling stress, birth order of siblings with a DD and TD sibling income were
Figure 2 displays the indirect effect of group membership (coded 0 = ID, 1 = ASD)
through sibling relationship attitudes when predicting aid provided by TD siblings (Panel A), TD
sibling depression (Panel B), and TD sibling stress (Panel C). The point estimate of the indirect
effect was -.93 (95% CI [-2.26, -.22]) when predicting TD sibling aid, 2.00 (95% CI [.52, 4.53])
when predicting TD sibling depression, and 1.52 (95% CI [.25, 3.61]) when predicting TD
sibling stress. No indirect effect was found when predicting TD sibling life satisfaction -1.16
(95% CI [-3.0, .004]). The negative coefficients between group membership and sibling
relationship attitudes reflect the Hypothesis 2 findings (that TD siblings of those with ID report
higher levels of positive sibling relationship attitudes compared to TD siblings of those with
ASD).
For these three TD sibling outcomes (aid, depression, stress), three additional post-hoc
analyses were conducted to examine indirect effects of group membership on sibling relationship
attitudes indirectly through each of the TD sibling outcomes. Despite the total effect of group
membership on sibling relationship attitudes, none of the indirect effects through the TD sibling
outcomes were significant. These additional analyses further bolster our confidence in the
9. Discussion
SIBLING RELATIONSHIP QUALITY 16
In this study, we found that TD siblings of individuals with ASD reported fewer positive
attitudes about their sibling relationship compared to TD siblings of individuals with ID. Across
the whole sample, sibling relationship attitudes accounted for significant variance over and
life satisfaction, and in TD sibling depressive symptoms and stress. Specifically, results
suggested that more positive sibling relationship attitudes were related to increased levels of aid
provided and life satisfaction and lower levels of depressive symptoms and stress. Despite the
challenges related to caring for a sibling with a disability described in previous research
(Dunigan & Connell, 2015; Tozer & Atkin, 2015), TD siblings in our sample who expressed
more positive attitudes about their sibling relationships also provided higher levels of aid to their
sibling, described being more satisfied with life, and reported fewer depressive and stress
symptoms.
TD siblings of those with ASD reported significantly fewer positive sibling relationship
attitudes. Multiple studies have compared child siblings of those with ASD to those with Down
Syndrome and other intellectual disabilities, and several differences have been observed. For
example, siblings of children with ASD often describe their sibling’s disability as stressful and as
having a negative impact on the sibling relationship (e.g., Petalas, Hastings, Nash, Dowey, &
Reilly, 2009; Ross & Cuskelly, 2006; Sage & Jegatheesan, 2010) and on their relationships with
friends (Petalas et al., 2009). TD siblings of individuals with ASD also report lower levels of
nurturance, intimacy, and prosocial behavior toward their sibling with ASD and increased
internalizing problems when compared to those with DS (Fisman, Wolf, Ellison, & Freeman,
2000; Kaminsky & Dewey, 2001). Alternatively, siblings of those with DS do not report the
aforementioned psychoscial problems as frequently (Kaminsky & Dewey, 2002), report higher
SIBLING RELATIONSHIP QUALITY 17
levels of relationship quality and more social support within the sibling relationship (Pollard et
al., 2013), and more overall positive views about their sibling’s disability (Mandleco & Webb,
2015). Many have suggested that there is something different about living with an individual
with ASD compared to living with individuals with other, similar disorders (Fisman et al., 2000;
Kaminsky & Dewey, 2001; Mascha & Boucher, 2006). The core deficits in social functioning
inherent in ASD often create interpersonal challenges, and these difficulties likely extend to
sibling relationships (Kaminsky & Dewey, 2001; Orsmond & Seltzer, 2000). The results of the
current study suggest that these distinct characteristics of ASD sibling relationship dyads appear
Finally, multiple indirect pathways through sibling relationship attitudes were identified.
These results indicate that there is an indirect effect of group membership on amount of aid
provided and TD sibling depressive symptoms and stress through sibling relationship attitudes.
Specifically, results indicate that TD siblings of those with ASD may be at greater risk for
depression and stress and for providing less aid/support due to lower levels of positive sibling
relationship attitudes. Again, these results support the notion that siblings of individuals with
ASD are at greater risk for negative outcomes when compared to siblings of individuals with ID
(Hodapp & Urbano, 2007; Orsmond & Seltzer, 2000) and that these effects may be explained, at
least in part, by sibling relationship attitudes. In contrast, group membership did not demonstrate
an indirect effect on life satisfaction through sibling relationship attitudes, perhaps because life
Previous research indicates that time spent with siblings with developmental disabilities
may often be spent providing instrumental support rather than engaging in close emotional and
interpersonal sibling relationship behaviors (Burbidge & Minnes, 2014). The unique nature of
SIBLING RELATIONSHIP QUALITY 18
individuals with ASD given that those affected with ASD may be even less likely to reciprocate
prosocial behavior. Nevertheless, these indirect pathways indicate that sibling relationship
attitudes may be a particularly salient point of intervention. According to the current results,
improvements in sibling relationship attitudes may lead to reductions in depression and stress
and increases in amount of aid provided, particularly among TD siblings of individuals with
ASD.
Several limitations should be considered when interpreting these results. The sample is
relatively small and data were collected in a way that may have led to sampling bias, thus
reducing the generalizability of results. The relatively wide sibling age range could confound the
findings due to differences in experiences of young adults versus middle-age adults. However,
age of TD siblings was statistically accounted for given the significant differences between the
groups and its relation with criterion variables. In addition, data indicate that some of the TD
siblings may have lived with both their parents and their sibling with a disability; this may have
introduced error given differences related to varied living arrangements. Moreover, a large
segment of the sample was female and previous research indicates that sisters may interact with
siblings with disabilities differently compared to brothers (Burke et al., 2012; Cridland, Jones,
Stoyles, Caputi, & Magee, 2015; Orsmond & Seltzer, 2000, 2009). Finally, many of the
respondents were recruited via organizations that provide support for those with disabilities and
their families. Thus, the current sample’s representation of the broader population may be less
than optimal.
SIBLING RELATIONSHIP QUALITY 19
The study’s cross-sectional design also limits conclusions that can be drawn. Larger,
more diverse longitudinal studies that yield contemporaneous data early in childhood and later in
life are necessary for achieving a more accurate assessment of sibling functioning. Also,
directionality and temporal relations among these variables cannot be determined. Although
sibling relationship attitudes was theorized as a predictor in the current analyses, the relations
between the variables of interest may be in the opposite direction. For example, it may be that
those siblings who provide high levels of aid to their sibling with a disability or who are
generally satisfied in life may then experience more positive attitudes about the sibling
relationship. However, we have higher confidence in the directionality of the indirect effects
given that diagnoses (i.e., group membership) were likely determined, in most cases, when
siblings were children and given that the tests for an indirect effect when reversing sibling
relationship attitudes with TD sibling outcomes in the model were all not significant.
Additionally, diagnoses of the siblings with disabilities were not independently confirmed, and
standardized measures of disability, behavior problems, and adaptive functioning were not
performed—all of which are additional domains that may influence sibling relationship attitudes
and outcomes in TD siblings. Future research would be strengthened by direct assessment of the
affected individuals so that diagnoses are confirmed and more thorough information about the
characteristics of the siblings can be gathered. Finally, data from multiple informants (e.g.,
multiple siblings, parents) would allow for a more comprehensive view of the constructs of
interest.
9.2. Conclusions
this study suggest that the attitudes possessed by TD siblings are important to consider when
SIBLING RELATIONSHIP QUALITY 20
understanding adult sibling outcomes. Specifically, data suggest that higher levels of positive
sibling relationship attitudes are related to TD siblings providing more aid/support to their
sibling with a disability, along with higher levels of general life satisfaction. More positive
sibling relationship attitudes also appear associated with lower levels of stress and depressive
symptoms among TD siblings. Consistent with previous child research (e.g., Mandleco & Webb,
2015), siblings of individuals with ASD report fewer positive sibling relationship attitudes
compared to siblings of individuals with ID without ASD. Finally, given the indirect effects of
group membership on aid/support provided, depressive symptoms, and stress through sibling
particularly for siblings of individuals with ASD. Although prior changes in public policy would
be needed, clinicians working with adult siblings of those with ASD may be able to work with
clients to improve their attitudes about the sibling relationship when targeting other psychosocial
outcomes. Despite this study’s limitations, the results provide promising clues for improving our
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Figure Captions:
Figure 1. Conceptual model of indirect effect between group membership and TD sibling
outcomes through sibling relationship attitudes.
Figure 2. Mediated outcomes on TD sibling aid/support provided (panel A), depression (panel
B), and stress (panel C) showing indirect effects of group membership through sibling
relationship attitudes. Note: Propensity scores were entered as a control variable for all three
panels to account for group differences in demographic characteristics. For panel A, birth order,
race (dichotomized: 1 = white, 0 = nonwhite), geographic distance, and sibling age difference
(absolute value) were additional covariates. For panel B, TD sibling marital status
(dichotomized: 1 = living with significant other, 0 = living alone) and TD sibling income were
additional covariates. For panel C, birth order and TD sibling income were additional covariates.
Unstandardized regression coefficients are reported. Statistics in brackets show the total effect of
the predictor on the outcome; statistics in parentheses show the direct effect of the predictor on
the outcome, after controlling for the indirect effect of the mediator. Each indirect effect
(depicted above each curved, dashed arrow) was significant based on an asymmetric 95%
confidence interval with 5000 resamples with replacement (Hayes, 2013).
SIBLING RELATIONSHIP QUALITY 28
Table 1
Groups
Total Sample ASD ID
(N = 82) (n = 45) (n = 37)
Variables M SD M SD M SD F d
DASS Depression 8.57 8.54 8.80 8.16 8.28 9.08 .08 .06
DASS Anxiety 5.56 6.64 5.42 7.02 5.73 6.24 .13 .05
DASS Stress 11.67 8.02 11.89 7.87 11.41 8.29 .00 .06
Total Aid 5.49 4.80 5.00 4.85 6.08 4.73 .93 .23
SLS Total 25.40 6.84 24.73 6.55 26.22 7.19 3.06 .22
LSRS Total 161.62 32.81 153.45 31.82 171.55 31.63 7.55** .57
Note. ASD = autism spectrum disorder; ID = intellectual disability (without autism); DASS =
Depression, Anxiety, and Stress Scale; Aid = Amount of aid/support provided by TD sibling;
SLS = Satisfaction with Life Scale; LSRS = Lifespan Sibling Relationship Scale. Group
differences between ASD and ID were examined using ANCOVA with propensity score as a
single covariate (analyses were repeated with individual covariates; results remained
unchanged).
** p < .01.
SIBLING RELATIONSHIP QUALITY 29
Table 2
1. 2. 3. 4. 5. 6.
1. DASS Depression -- .60** .66** .09 -.36** -.28*
2. DASS Anxiety -- .65** .21 -.15 -.07
3. DASS Stress -- .18 -.16 -.13
4. Total Aid -- .03 .41**
5. SLS Total -- .31**
6. LSRS Total --
Note. DASS = Depression, Anxiety, and Stress Scale; Aid = Amount of aid provided by TD
sibling; SLS = Satisfaction with Life Scale; LSRS = Lifespan Sibling Relationship Scale; SD =
Standard deviation.
** p < .01. * p < .05.
SIBLING RELATIONSHIP QUALITY 30
Table 3
Correlations between Possible Control Variables and Criterion Variables (Total Sample)
Criterion Variables
Possible Control Variables DASS DASS DASS Total SLS LSRS
Dep. Anxiety Stress Aid Total Total
Sib w/ Dis Age -.09 -.13 -.01 .07 -.16 -.003
Sib w/ Dis Gender -.16 -.15 -.15 -.13 -.04 -.10
Sib w/ Dis Birth Order .03 -.03 .26* .22* .13 .18
Distance from Sib w/ Dis -.05 -.03 -.11 .42** -.08 .19
TD Sibling Gender -.003 -.06 -.06 -.16 -.004 -.003
TD Sibling Age -.12 -.15 .00 .19 -.01 .11
TD Sibling Birth Order .08 .06 -.06 .12 -.11 .07
TD Sibling Race (Dich.) -.05 -.05 .06 -.31** .14 -.21
TD Sibling Education -.08 -.06 .05 -.09 -.08 .05
TD Sibling Income -.25* -.37** -.26* -.13 -.05 -.18
Childhood Family Size .16 .07 .17 .19 -.06 .07
TD Sib Marital Stat (Dich) -.31** -.19 -.12 -.01 .11 .007
Age Disc. (Abs. Value) -.03 -.01 -.08 .23* .26* .19
Note. Sib w/ Dis = Sibling with a disability; TD = Typically-developing; Dich = Dichotomized;
Abs. Value = Absolute Value; DASS = Depression, Anxiety and Stress Scale; SLS = Satisfaction
with Life Scale; Aid = Amount of aid provided by TD sibling; LSRS = Lifespan Sibling
Relationship Scale. Race coded as 0 = nonwhite, 1 = white; Marital status coded as 0 = living
alone, 1 = living with a significant other.
** p < .01. * p < .05.
SIBLING RELATIONSHIP QUALITY 31
Table 4
Groups
Total Sample ASD ID
(N = 82) (n = 45) (n = 37)
Possible Control Variables M SD M SD M SD t d
Sib w/ Dis Age 30.44 11.43 26.49 8.55 35.24 12.71 3.58** .81
Sib w/ Dis Gender 1.33 .47 1.20 .41 1.49 .51 2.79** .62
Sib w/ Dis Birth Order 2.37 1.18 2.29 .90 2.46 1.46 .62 .14
Distance From Sib w/ Dis 2.24 1.22 2.29 1.27 2.19 1.16 -.37 .08
TD Sib Gender 1.84 .37 1.82 .39 1.86 .35 .53 .11
TD Sib Age 32.52 12.43 29.42 11.08 36.30 13.07 2.54* .57
TD Sib Birth Order 1.93 1.03 1.60 .84 2.32 1.11 3.28** .73
TD Sib Race (Dich) .88 .33 .84 .37 .92 .28 1.05 .24
TD Sib Education 5.93 .84 5.91 .82 5.95 .88 .19 .05
TD Sib Income 7.14 2.01 7.00 2.21 7.31 1.74 .70 .16
Childhood Family Size 5.12 1.47 4.71 .82 5.64 1.90 2.74** .64
TD Sib marital status (Dich) .56 .50 .56 .50 .57 .50 .11 .02
Age Discrepancy (Abs. Value) 4.67 4.29 4.71 4.97 4.62 3.34 -.10 .02
Note. ASD = autism spectrum disorder; ID = intellectual disability (without autism); Sib w/ Dis
= sibling with disability; TD Sib = typically-developing sibling; Dich = dichotomized; Abs.
Value = absolute value; Gender coded as 1 = male, 2 = female; Race coded as 0 = nonwhite, 1 =
white; Marital status coded as 0 = living alone, 1 = living with a significant other.
** p < .01. * p < .05.
SIBLING RELATIONSHIP QUALITY 32
Table 5
Results of Multiple Regression Analyses of Sibling Relationship Attitudes Predicting Aid/Support Provided by TD Siblings, TD
Siblings’ Life Satisfaction, and Depression, Anxiety, and Stress in TD Siblings (Total Sample)
Criterion Variables
Predictor Variables Total Aid SLS Total Depression Anxiety Stress
Model 1
Age Discrepancy (Abs. Value) .17 .26* -- -- --
Distance from Sib w/ Dis .34** -- -- -- --
Sib w/ Dis Birth Order .18 -- -- -- .25*
TD Sibling Race (Dich) -.18 -- -- -- --
TD Sibling Income -- -- -.18 -.37** -.27*
TD Sibling Marital Stat (Dich) -- -- -.28* -- --
R2 (df) .28 (4,77)*** .07 (1,80)* .14 (2,78)** .14 (1,79)** .13 (2,78)**
Model 2
Sibling Relationship Attitudes .27** .27* -.31** -.14 -.23*
ΔR2 (df) .07 (1,76)** .07 (1,79)* .09 (1,77)** .02 (1,78) .05 (1,77)*
Note. Abs. Value = absolute value; Sib w/ Dis = sibling with disability; TD = Typically-developing; Race coded as 1 = white, 0 =
nonwhite; Marital Status coded as 0 = living alone, 1 = living with a significant other. Standardized beta-weights reported for each
predictor. Degrees of freedom reported in parentheses following each R2 value. Dashes indicate that control variables are not
applicable for respective analyses.
*** p < .001. ** p < .01. * p < .05.
Figure 1
A
Figure 2